Abstract
Congenital bladder underdevelopment has detrimental genitourinary effects. We present
a male infant with declining renal function, recurrent urinary tract infections, and
epididymo-orchitis, in the setting of bilateral high grade hydronephrosis and vesicoureteral
reflux. Cystoscopic evaluation revealed the presumed “bladder” to be a massively dilated
prostatic urethra. The small dysplastic “true bladder” was found at the anterior surface
of the prostatic urethra with massively dilated ureteral orifices. Temporizing diversion
was performed in the form of bilateral cutaneous ureterostomies, with an ultimate
plan for reconstructive bladder surgery. This case presents diagnostic challenges
utilizing current modalities due to a massively dilated prostatic urethra in the rare
case of bladder dysplasia.
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Article info
Publication history
Published online: September 27, 2022
Accepted:
August 29,
2022
Received:
August 17,
2022
Identification
Copyright
© 2022 Elsevier Inc. All rights reserved.
